LEAD PROJECT 1: PHENYLKETONURIA (PKU)

NIH RePORTER · NIH · U19 · $1,419,953 · view on reporter.nih.gov ↗

Abstract

PROJECT SUMMARY Phenylketonuria (PKU) is an autosomal recessive disorder caused by mutations in the gene encoding phenylalanine hydroxylase (PAH), resulting in the accumulation of phenylalanine (Phe) to neurotoxic levels. Among the five most frequently occurring pathogenic PAH variants worldwide is the c.842C>T (P281L) mutation, which is amenable to adenine base editing. The current treatment options have significant limitations—a strict low-Phe diet to which many patients find it difficult to adhere, and a daily injectable enzyme therapy with a substantial risk of anaphylaxis. Lead Project 1 will focus on a lipid nanoparticle (LNP)-based adenine base editing treatment for PKU in patients with the P281L variant, with the aim to file an IND application by the end of the five-year funding period and begin a phase 1/2 clinical trial soon afterwards.

Key facts

NIH application ID
10896260
Project number
5U19NS132301-02
Recipient
CHILDREN'S HOSP OF PHILADELPHIA
Principal Investigator
Kiran Musunuru
Activity code
U19
Funding institute
NIH
Fiscal year
2024
Award amount
$1,419,953
Award type
5
Project period
2023-08-01 → 2028-07-31